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´OL@ # /B޻L/ά곪4`%o_ <#%F@EtlD} KLe3^jpoH3ޏbD`o^_"{yŽn:`OAǹxy>-M< endstream endobj 35 0 obj <>stream hތVKo[E]~v yݹRUhn%֪V犹g6K=^0Z>"6/xqK|<;A3' (DR폻(o훔cɚ;?$}!(<<5AH)__t ꈚP|m_RL%Ge}XEoΦwv2 !d%ui3غnGla-.voڷw%UчnF3#7Y( .el.?.)2duAe8!Х;1t)"k& WkAMdà&y<6êj(kv MVFWg0fj$az`1{dhguM!lpd-'uV<6*o7C&X94 Σ{RGm_:kS$>stream 2022-07-08T10:01:20+08:00 2022-07-08T10:01:18+08:00 2022-07-08T10:01:20+08:00 Acrobat PDFMaker 11 Word 版 uuid:08d4b86e-cc66-445c-a601-92b8602f28d5 uuid:e88c26fe-b590-442e-9c2f-775b720b0136 371 application/pdf 儿童EB病毒阳性T/NK细胞淋巴组织增殖性疾病21例临床病理特点及预后分析 目的:分析儿童EB病毒阳性T/NK细胞淋巴组织增殖性疾病临床病理特征及预后。方法:回顾性分析了21例儿童EB病毒阳性T/NK细胞淋巴组织增殖性疾病的临床病理资料,采用Kaplan-Meier法分析预后影响因素。结果:21例儿童EBV-T/NK-LPDs中男孩12例,女孩9例,发病年龄2~14岁(中位年龄8岁)。CAEBV 9例,HV-LPD 8例,CSEBV + TCL 4例,发病年龄分别为7~14岁(中位年龄10岁),2~12岁(中位年龄6岁)、6~12岁(中位年龄8.5岁)。临床主要表现为发热(17/21)、肝脏肿大(15/21)、脾脏肿大(14/21)、淋巴结肿大(11/21)和皮疹(10/21),伴全血细胞减少(10/21)、肝功能异常(9/21)、凝血功能障碍(7/21)、HLH (7/21)及肾功能异常(3/21)。21例患儿全血EBV-DNA拷贝数明显升高,超过104 copies/ml。组织病理特点为EB病毒感染的淋巴细胞增生,细胞形态多样。免疫组化:CD3、TIA-1阳性,部分合并CD56阳性。EBER原位杂交阳性。Ki-67增殖指数10%~90%。2例CAEBV、2例CSEBV + TCL及1例HV-LPD患儿检测到TCRγ基因克隆性重排。治疗策略包括抗病毒、糖皮质激素、联合化疗和HLH方案,1例患儿接受造血干细胞移植。随访20例患儿,随访时间0.3~59个月,死亡16例,存活4例。单因素分析结果:血小板减少(P = 0.013)、LDH升高(P = 0.003)、胆红素升高(P = 0)、肾功能异常(P = 0.02)、凝血功能障碍(P = 0)、合并HLH (P = 0)是预后不良的影响因素。结论:儿童EBV-T/NK-LPDs临床罕见,侵袭性强,接受抗病毒、糖皮质激素或按HLH方案治疗,病死率仍高。血小板减少、LDH升高、胆红素升高、肾功能异常、凝血功能障碍、合并HLH与不良预后相关。 杨梅,窦颖,管贤敏,郭玉霞,温贤浩,于洁 Adobe PDF Library 11.0 儿童EB病毒阳性T/NK细胞淋巴组织增殖性疾病,慢性活动性EB病毒感染,种痘水疱病样淋巴组织增生性疾病,儿童系统性EB病毒阳性T细胞淋巴瘤,预后 D:20220708020014 çł®çı—ï¼ı勃枒嗿童EB犖毙音敧T/NK练腞淉巴绗ç»⁄增殌敧猾犖临åº−犖璃盹徆å‘−é¢—å’”ã•‡æŒ¹æ³Łï¼ıåłžé¡¾æ•§å‹ƒæž’äºƒ21侉嗿童EB犖毙音敧T/NK练腞淉巴绗ç»⁄增殌敧猾犖çı—临åº−犖璃赗挎$é⁄⁄çfl¨Kaplan-Meieræ³Łå‹ƒæž’é¢—å’”å½±åfi“åł€ç´€ã•‡ç»fiæžœï¼ı21侉嗿童EBV-T/NK-LPDsä¸�çfl·å�©12侉$女å�©9侉$呂犖年龗2~14岆(ä¸�体年龗8岆)㕇CAEBV 9侉$HV-LPD 8侉$CSEBV + TCL 4侉$呂犖年龗勃勫为7~14岆(ä¸�体年龗10岆)$2~12岆(ä¸�体年龗6岆)㕆6~12岆(ä¸�体年龗8.5岆)㕇临åº−主覆表田为呂ç…�(17/21)㕆臚藑臿大(15/21)㕆藾藑臿大(14/21)㕆淉巴ç»fi臿大(11/21)噄çı®çŒ¹(10/21)$伴喨衕练腞å⁄‘å°‚(10/21)㕆臚å−�腽弇常(9/21)㕆å⁄šè¡•å−�è…½éıœç¢“(7/21)㕆HLH (7/21)å‘−臾å−�腽弇常(3/21)㕇21侉懣嗿喨衕EBV-DNAæ‰·è´šæŁ°æŸ”æŸ¾å“⁄髟$趖è¿⁄104 copies/ml㕇绗ç»⁄犖璃盹燹为EB犖毙æ—�æ�fiçı—淉巴练腞增çfl�$练腞形敆å¤ı怷㕇喓猫绗儌ï¼ıCD3㕆TIA-1音敧$酨勃咋并CD56音敧㕇EBERå”�体暇交音敧㕇Ki-67增殌æ„⁄æŁ°10%~90%㕇2侉CAEBV㕆2侉CSEBV + TCLå‘−1侉HV-LPD懣嗿棕浉勰TCRγå�ºåł€å–‰éıƒæ•§é⁄“攙㕇治猊ç�ŒçŁ¥å„–æ‰¬æ−ŠçŠ–æ¯™ã•†ç³Œçı®è´¨æ¿•紀㕆è†fl咋儌猊噄HLH挹桋$1侉懣嗿攥告镀衕干练腞移椓㕇éı‘访20侉懣嗿$éı‘访抶銴0.3~59个朋$æ�»äº¡16侉$å�Ÿæ´»4ä¾‰ã•‡å“Łåł€ç´€å‹ƒæž’ç»fiæžœï¼ıè¡•å°‘æš¿å⁄‘å°‚(P = 0.013)㕆LDHå“⁄髟(P = 0.003)㕆腃红紀å“⁄髟(P = 0)㕆臾å−�腽弇常(P = 0.02)㕆å⁄šè¡•å−�è…½éıœç¢“(P = 0)㕆咋并HLH (P = 0)柯颗咔专蛯çı—å½±åfi“åł€ç´€ã•‡ç»fi论ï¼ıå—¿ç«¥EBV-T/NK-LPDs临åº−ç½Łè§†ï¼„ä¾µè¢�敧强$攥告æ−ŠçŠ–æ¯™ã•†ç³Œçı®è´¨æ¿•紀拌愛HLH挹桋治猊$犖æ�»ç”⁄仓髟㕇衕少暿å⁄‘専㕆LDHå“⁄髟㕆腃红紀å“⁄髟㕆臾å−�腽弇常㕆å⁄šè¡•å−�è…½éıœç¢“㕆咋并HLHä¸”ä¸“è›¯é¢—å’”çł¸å–³ã•‡ endstream endobj 37 0 obj <>stream h22T0Pw/+QL)626)I12Q!vvK endstream endobj 38 0 obj <>stream hޔUmLe1n HtV}Z -0nb+uld'h+-^cf1 .S2bb\4hdC$S8O=]i֘zgn47PL+C3uŢDM_.4]xJ8C1(hƽSi=ޛ Ǧ$wٌfd5ac]IJvz (|ȋFȎ!M"842FGAF@D ~9&`y/:(L~_l27w߾p?s#zɢG'^W$]Aܐ+!kEOܷG|xjŜ{8 Tތ }o aaz0B6ZDσD a3X{'!臭 euq%Y+g58ˑRȝŌGG,2gsm.%ª44"?< FnGKhl/I ]*Ӡ eE0옓;ȉ%%r`%\ N4;dMe_dZbRM2oڗt"kU&`MɼCS jʷԶ7)15iggL'{+~A Eɖ^)6g[ͱ8rC7*".+T\J {q;H?1u8Ο=WJC#ᡷٵU5NZ+:4HHe6? 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